Abstract Rationale: Hemolymphangioma is a benign tumor comprised of the newly-formed lymph spaces and blood vessels, which can usually be found in the head and neck of the affected children. There are few reports regarding cases with hemolymphangioma in small intestine, spleen, esophagus, and other organs. Patient concerns: Herein, a 55-year-old woman was presented in this study, she had complained of discomfort in the right upper abdomen for 2 months, and was discovered with a space-occupying lesion in proximal jejunum on computed tomography (CT). Eventually, the lesions were confirmed through double-balloon enteroscopy (DBE) to be located in the jejunum 60 cm away from the Treitz ligament. Diagnose: Subsequently, the small intestine was partially resected, and postoperative pathology had confirmed the diagnosis of small intestinal hemolymphangioma. Interventions: Excisional surgery of the lesion was planned. On surgery, the lesions were discovered to be about 3∗3 cm to 2∗2 cm when engorged the superficial vessels. No enlarged lymph nodes were seen at the root of the mesentery, and no obvious lesion was observed in the remaining small intestine. Outcomes: Follow-up for 6 months showed no recurrence. Lessons: Hemolymphangioma lacks typical clinical symptoms, and the correct preoperative diagnosis of hemolymphangioma remains challenging. Due to the increasing use of endoscopic diagnostic techniques, it is expected that hemolymphangioma in gastrointestinal tract may be detected and endoluminal located before surgery more feasibly. This case report aimed to highlight the contributions of CT and DBE to an accurate preoperative diagnosis and surgical strategy planning.

中文翻译：

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空肠血淋巴管瘤

摘要 基本原理：血管瘤是一种由新生淋巴腔和血管组成的良性肿瘤，多见于受累儿童的头颈部。小肠、脾脏、食道等器官的血管瘤病例报道较少。患者关注点：本研究中介绍了一名 55 岁女性，她主诉右上腹部不适 2 个月，在计算机断层扫描 (CT) 上发现近端空肠占位性病变. 最终，通过双气囊小肠镜（DBE）确认病变位于距 Treitz 韧带 60 cm 的空肠。诊断：随后，小肠被部分切除，术后病理证实小肠血管瘤的诊断。干预：计划对病变进行切除手术。手术时发现病变约 3*3 cm 至 2*2 cm，充血浅表血管。肠系膜根部未见肿大淋巴结，其余小肠未见明显病变。结果：随访6个月未见复发。经验教训：血淋巴管瘤缺乏典型的临床症状，对血淋巴管瘤的正确术前诊断仍然具有挑战性。由于越来越多地使用内窥镜诊断技术，预计在手术前可以检测到胃肠道中的血管瘤并在腔内定位更可行。